Disrupted Superior Collicular Activity May Reveal Cervical Dystonia Disease Pathomechanisms

Eavan McGovern, St Vincent's University Hospital
Owen Killian, St Vincent's University Hospital
Shruti Narasimham, Trinity College Dublin, Ireland
Brendan Quinlivan, Trinity College Dublin Ireland
John Butler, Technological University Dublin
Rebecca Beck, Trinity College Dublin Ireland
Ines Beiser, St Vincent's University Hospital
Laura Williams, St Vincent's University Hospital
Ronan P. Kileen, St. Vincent’s University Hospital
Michael Farrell, St. Vincent’s University Hospital
Sean O'Riordan, St. Vincent’s University Hospital
Richard B. Reilly, Trinity College Dublin Ireland
Michael Hutchinson, St. Vincent’s University Hospital

Document Type Article

Scientific Reports volume 7, Article number: 16753 (2017)

Abstract

Cervical dystonia is a common neurological movement disorder characterised by muscle contractions causing abnormal movements and postures afecting the head and neck. The neural networks underpinning this condition are incompletely understood. While animal models suggest a role for the superior colliculus in its pathophysiology, this link has yet to be established in humans. The present experiment was designed to test the hypothesis that disrupted superior collicular processing is evident in afected patients and in relatives harbouring a disease-specifc endophenotype (abnormal temporal discrimination). The study participants were 16 cervical dystonia patients, 16 unafected frst-degree relatives with abnormal temporal discrimination, 16 unafected frst-degree relatives with normal temporal discrimination and 16 healthy controls. The response of participant’s superior colliculi to looming stimuli was assessed by functional magnetic resonance imaging. Cervical dystonia patients and relatives with abnormal temporal discrimination demonstrated (i) signifcantly reduced superior collicular activation for whole brain and region of interest analysis; (ii) a statistically signifcant negative correlation between temporal discrimination threshold and superior collicular peak values. Our results support the hypothesis that disrupted superior collicular processing is involved in the pathogenesis of cervical dystonia. These fndings, which align with animal models of cervical dystonia, shed new light on pathomechanisms in humans.